RARE CASE OF BLAND WHITE-GARLAND SYNDROME WITH MYOCARDIAL INFARCTION IN PAEDIATRICS

Munnaza Saleem, Syed Sajid Hussain Shah, Tahir Mehmood

Abstract


A 3.5 months old female infant presented with acute history of loose motions, fever and irritability for 5 days. The infant had history of respiratory distress since birth that exaggerated while feeding along with sweating and increased milk intake. Patient had poor weight gain. On investigations she was found to have anomalous origin of the left coronary artery from the left pulmonary artery (ALCAPA) with dilated cardiomyopathy and anterior wall myocardial infarction which is a very rare diagnosis in paediatrics and very rare condition diagnosed in our settings.

Keywords: Anomalous origin, coronary artery, myocardial infarction.

Full Text:

PDF

References


Perloff JK, editor. The clinical recognition of congenital heart disease. 4th ed. Philadelphia: WB Saunders;1994.

Bland EF, White PD, Garland J. Congenital anomalies of the coronary arteries: report of an unusual case associated with cardiac hypertrophy. Am Heart J 1933;8:787–801.

Wesselhoeft H, Fawcett JS, Johnson AL. Anomalous origin of the left coronary artery from the pulmonary trunk. Its clinical spectrum, pathology and pathophysiology based on a review of 140 cases with seven further cases. Circulation 1968;38:403–25.

Celermajer DS, Sholler GF, Howman-Giles R, Celermajer JM. Myocardial infarcton in childhood: clinical analysis of 17 cases and medium term follow up of survivors. Br Heart J 1991;65:332–6.

Wollenek G, Damanig E, Salzer-Mufar U, Havel M, Wimmer M, Wolner E. Anomalous origin of the left coronary artery: a review of surgical management in 13 patients. J Cardiovasc Surg 1993;34:399–405.

Edwards JE. The direction of blood flow in coronary arteries arising from the pulmonary trunk (editorial). Circulation 1964;29:163–6.

Purut CM, Sabiston DC Jr. Origin of the left coronary artery from the pulmonary artery in older adults. J Thorac Cardiovasc Surg 1991;102:566–70.

Arsan S, Naseri E, Keser N. An adult case of Bland-White-Garland syndrome with huge coronary artery aneurysm. Ann Thorac Surg 1999;68(5):1832–3.

Laborde F, Marchand M, Leca F, Jarreau MM, Dequirot A, Hazan E. Surgical treatment of anomalous origin of the left coronary artery in infancy and childhood. Early and late results in 20 consecutive cases. J Thorac Cardiovasc Surg 1981;82:423–8.

Alexi-Meskishvili V, Berger F, Weng Y, Lange PE, Hetzer R. Anomalous origin of the left coronary artery from the pulmonary artery in adults. J Card Surg 1995;10:309–15.


Refbacks

  • There are currently no refbacks.


Contact Number: +92-992-382571

email: [jamc] [@] [ayubmed.edu.pk]